Autosomal dominant adult-onset proximal spinal muscular atrophy

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ORPHA:209335OMIM:182980G12.1
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14Active trials33Specialists8Treatment centers

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UniteRare data is sourced from FDA.gov, ClinicalTrials.gov, Orphanet, OMIM, and NORD.
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Overview

Autosomal dominant adult-onset proximal spinal muscular atrophy (also known as adult-onset proximal SMA or late-onset SMA type 4) is a rare neuromuscular disorder characterized by progressive degeneration of the lower motor neurons in the spinal cord. Unlike the more common childhood-onset forms of spinal muscular atrophy, this condition manifests in adulthood, typically after the age of 30, and follows an autosomal dominant inheritance pattern rather than the autosomal recessive pattern seen in classical SMA caused by SMN1 mutations. The disease primarily affects the motor neurons that control voluntary muscles, particularly those closest to the trunk of the body (proximal muscles). Patients typically present with slowly progressive, symmetric weakness and wasting of the proximal limb muscles, especially in the legs and hip girdle region. Symptoms may include difficulty climbing stairs, rising from a seated position, and walking. Fasciculations (muscle twitching) and muscle cramps may also be observed. Deep tendon reflexes are often reduced or absent. The disease generally progresses slowly, and most affected individuals retain the ability to walk for many years, though some may eventually require mobility aids. There is currently no cure or disease-modifying treatment specifically approved for this form of SMA. Management is primarily supportive and symptomatic, including physical therapy to maintain muscle strength and mobility, occupational therapy, and orthopedic interventions as needed. The therapies approved for SMN1-related SMA (such as nusinersen, onasemnogene abeparvovec, and risdiplam) are not indicated for this genetically distinct condition. Regular monitoring by a multidisciplinary team including neurologists and rehabilitation specialists is recommended to optimize quality of life.

Also known as:

Clinical phenotype terms— hover any for plain English:

EMG: neuropathic changesHP:0003445Proximal amyotrophyHP:0007126Shuffling gaitHP:0002362Bulbar signsHP:0002483
Inheritance

Autosomal dominant

Passed on from just one parent; each child has about a 50% chance of inheriting it

Age of Onset

Adult

Begins in adulthood (age 18 or older)

Orphanet ↗OMIM ↗NORD ↗

FDA & Trial Timeline

10 events
Jan 2028Double-Blind Clinical Trial of Subthalamic Nucleus Deep Brain Stimulation in Early-Stage Parkinson's Disease

Mallory Hacker — NA

TrialNOT YET RECRUITING
Sep 2026A Study to Learn About the Safety and Effects of Salanersen (BIIB115) When Given to Babies With Spinal Muscular Atrophy (SMA) Who Were Previously Treated With Onasemnogene Abeparvovec

Biogen — PHASE3

TrialNOT YET RECRUITING
Jul 2026ASsessing The REAl-world Safety & Effectiveness of Spinal Muscular Atrophy Participants Treated With Intrathecal Onasemnogene Abeparvovec-brve (OAV101B) (ITVISMA®): A U.S. Pragmatic Multicenter Study (STREAM)

Novartis Pharmaceuticals — PHASE4

TrialNOT YET RECRUITING
Apr 2026A Study to Learn About Salanersen's (BIIB115) Effects on Movement and Its Safety in Participants Aged 15 to 60 Years With Spinal Muscular Atrophy (SMA) Who Are Either New to SMA Treatment or Were Previously Treated With Risdiplam

Biogen — PHASE3

TrialNOT YET RECRUITING
Mar 2026Safety and Feasibility of a Self-Learning Bolus Calculator With Simplified Meal Announcement in Adolescents With Type 1 Diabetes Using Automated Insulin Delivery

Anas El Fathi — NA

TrialRECRUITING
Jan 2026The Effect of rTMS Over the SMA on Gait Performance in Parkinson's Disease

The Hong Kong Polytechnic University — NA

TrialNOT YET RECRUITING
Dec 2025prTMS as an Intervention for Bradykinesia in Parkinson's Disease

Danish Research Centre for Magnetic Resonance — NA

TrialRECRUITING
Sep 2025Safety, Usability, and Effectiveness of a Gait Exoskeleton for Children and Adolescents With Neurodevelopmental Disorders.

MarsiBionics — NA

TrialNOT YET RECRUITING
Sep 2025A Study to Evaluate How Apitegromab Works in Subjects Who Are Less Than 2 Years Old and Have Spinal Muscular Atrophy

Scholar Rock, Inc. — PHASE2

TrialRECRUITING
Jul 2025Study of the Reproducibility of the French Version of the Modified SMAFRS Scale

Institut de Myologie, France

TrialRECRUITING

Data sourced from FDA regulatory filings and ClinicalTrials.gov. Updated periodically.

Treatments

No FDA-approved treatments are currently listed for Autosomal dominant adult-onset proximal spinal muscular atrophy.

14 clinical trialsare actively recruiting — trials can provide access to cutting-edge therapies.

View clinical trials →

Clinical Trials

14 recruitingView all trials with filters →
Phase 21 trial
A Study to Evaluate How Apitegromab Works in Subjects Who Are Less Than 2 Years Old and Have Spinal Muscular Atrophy
Phase 2
Actively Recruiting
· Sites: Phoenix, Arizona; Orange, California +21 more · Age: 02 yrs
N/A8 trials
NuroSleeve Powered Brace & Stimulation System to Restore Arm Function
N/A
Active
· Sites: Wilmington, Delaware; Philadelphia, Pennsylvania · Age: 499 yrs
Spinal Cord Stimulation for the Treatment of Motor Deficits in People With Spinal Muscular Atrophy - Upper Limb
N/A
Active
PI: Marco Capogrosso (University of Pittsburgh) · Sites: Pittsburgh, Pennsylvania · Age: 1665 yrs
Acceptability, Feasibility, Safety and Efficacy of a Optimized Rehabilitation Program for Treated Patients With Spinal Muscular Atrophy (SMA).
N/A
Active
PI: Charlotte Lilien (University of Oxford, Department of Paediatrics) · Sites: Oxford, Oxfordshire · Age: 110 yrs
A Head-to-head Study Comparing the Functional Value of Two Models of Robotically Assisted Rehabilitation in SMA (Spinal Muscular Atrophy) Patients
N/A
Actively Recruiting
PI: Marek Jóźwiak (Wiktor Dega University Orthopedic and Rehabilitati) · Sites: Poznan · Age: 021 yrs
Outpatient Rehabilitation Intervention for Young Children With SMA
N/A
Actively Recruiting
· Sites: Toronto, Ontario · Age: 06 yrs
Study of an Intrathecal Port and Catheter System for Subjects With Spinal Muscular Atrophy
N/A
Actively Recruiting
· Sites: Phoenix, Arizona; Orange, California +19 more · Age: 399 yrs
COMMAND Early Feasibility Study: Implantable BCI to Control a Digital Device for People With Paralysis
N/A
Active
· Sites: Buffalo, New York; New York, New York +1 more · Age: 2175 yrs
High-intensity Interval Training in Patients With Spinal Muscular Atrophy
N/A
Actively Recruiting
PI: John Vissing, prof. MD (Rigshospitalet, Denmark) · Sites: Copenhagen · Age: 1599 yrs
Other4 trials
A Review of the Management and Outcomes of Children With SMA in the West Midlands During 2017-2022
Actively Recruiting
· Sites: Birmingham, Shropshire; Oswestry, Shropshire · Age: 016 yrs
Swiss Registry for Neuromuscular Disorders
Actively Recruiting
PI: Claudia E Kuehni, Prof. MD (Institute of Social and Preventive Medicine (ISPM)) · Sites: Aarau, Canton of Aargau; Bellinzona, Canton Ticino +17 more
Study of the Reproducibility of the French Version of the Modified SMAFRS Scale
Actively Recruiting
· Sites: Paris · Age: 018 yrs
French Register of Patients With Spinal Muscular Atrophy
Actively Recruiting
PI: Susana Quijano-Roy, MD, PhD (Unité neuromusculaire, Service de Neurologie et Ré) · Sites: Garches

Specialists

Showing 25 of 33View all specialists →
EM
Eugenio Mercuri, MD
Genova
Specialist

Rare Disease Specialist

PI on 3 active trials
LM
Laurent Servais, MD
Specialist
PI on 6 active trials1 Autosomal dominant adult-onset proximal spinal muscular atrophy publication
RP
Richard S Bedlack, MD, PhD
DURHAM, NC
Specialist
PI on 2 active trials
KM
Kenneth H Fischbeck, M.D.
BETHESDA, MD
Specialist
PI on 6 active trials
MM
May Orfali, MD
Specialist
PI on 3 active trials
JE
Jacqueline Montes, Pt, EdD
New York, New York
Specialist

Rare Disease Specialist

PI on 5 active trials
OP
Otávio Berwanger, PhD
Buenos Aires, Buenos Aires F.D.
Specialist

Rare Disease Specialist

PI on 3 active trials
SP
Susana QUIJANO-ROY, MD, PhD
Specialist
PI on 3 active trials
MM
Melodi Pirzada, MD
MINEOLA, NY
Specialist
PI on 4 active trials
DW
Dr Ching H. Wang
Specialist
PI on 2 active trials528 Autosomal dominant adult-onset proximal spinal muscular atrophy publications
MM
Matthew Harms, MD
LAWRENCE, KS
Specialist
PI on 2 active trials
WM
Walter Truong, MD
ST. PAUL, MN
Specialist
PI on 2 active trials1 Autosomal dominant adult-onset proximal spinal muscular atrophy publication
EM
Emmanuel ROZE, MD
Specialist
PI on 2 active trials
MC
Marco Capogrosso
Specialist
PI on 2 active trials
MB
Minal J Bhanushali
PALO ALTO, CA
Specialist
PI on 1 active trial
CL
Charlotte Lilien
Specialist
PI on 1 active trial
YS
Yi-Ning su
Specialist
PI on 2 active trials
CT
Chayada Tangshewinsirikul
Specialist
PI on 1 active trial
JK
John T Kissel
CHURCHVILLE, NY
Specialist
PI on 1 active trial
LC
Liang-Wey Chang
Specialist
PI on 1 active trial
SM
Samra Hamzic, MA
Specialist
PI on 1 active trial
BZ
Bruno A Zanfini
Specialist
PI on 1 active trial
AS
Andriy V. Shatillo
Specialist
PI on 1 active trial

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to Autosomal dominant adult-onset proximal spinal muscular atrophy.

Search all travel grants →NORD Financial Assistance ↗

Community

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Latest news about Autosomal dominant adult-onset proximal spinal muscular atrophy

Disease timeline:

New recruiting trial: Long Term Trajectories of SMA Patients Receiving or Not Disease-modifying Treatments

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: Active NBS Study: Decentralised Monitoring Motor Development in Children With Duchenne Muscular Dystrophy or Spinal Muscular Atrophy Identified by Newborn Screening

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: High-intensity Interval Training in Patients With Spinal Muscular Atrophy

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: A Review of the Management and Outcomes of Children With SMA in the West Midlands During 2017-2022

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: Real World Clinical Effectiveness & Safety of Vesemnogene Lantuparvovec for Spinal Muscular Atrophy (SMA) in Low-middle Income Countries (LMIC).

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: Test of Aquatic Mobility of SMA Infants

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: Evaluation of Safety and Efficacy of Gene Therapy Drug in the Treatment of Spinal Muscular Atrophy (SMA) Type 1 Patients

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: prTMS as an Intervention for Bradykinesia in Parkinson's Disease

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: A Registry Based Randomized-Controlled Trial of an Upper Limb Exergaming Intervention for Children and Adolescents With Spinal Muscular Atrophy

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

New recruiting trial: rTMS as an Intervention for Levodopa-induced Dyskinesia

A new clinical trial is recruiting patients for Autosomal dominant adult-onset proximal spinal muscular atrophy

Caregiver Resources

NORD Caregiver Resources

Support, advocacy, and financial assistance for caregivers of rare disease patients.

Mental Health Support

Rare disease caregiving can be isolating. Connect with counseling and peer support.

Family & Caregiver Grants

Financial assistance programs specifically for caregivers of rare disease patients.

Social Security Disability

Learn how rare disease patients may qualify for SSDI/SSI benefits.

Common questions about Autosomal dominant adult-onset proximal spinal muscular atrophy

What is Autosomal dominant adult-onset proximal spinal muscular atrophy?

Autosomal dominant adult-onset proximal spinal muscular atrophy (also known as adult-onset proximal SMA or late-onset SMA type 4) is a rare neuromuscular disorder characterized by progressive degeneration of the lower motor neurons in the spinal cord. Unlike the more common childhood-onset forms of spinal muscular atrophy, this condition manifests in adulthood, typically after the age of 30, and follows an autosomal dominant inheritance pattern rather than the autosomal recessive pattern seen in classical SMA caused by SMN1 mutations. The disease primarily affects the motor neurons that contr

How is Autosomal dominant adult-onset proximal spinal muscular atrophy inherited?

Autosomal dominant adult-onset proximal spinal muscular atrophy follows a autosomal dominant inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Autosomal dominant adult-onset proximal spinal muscular atrophy typically begin?

Typical onset of Autosomal dominant adult-onset proximal spinal muscular atrophy is adult. Age of onset can vary across affected individuals.

Are there clinical trials for Autosomal dominant adult-onset proximal spinal muscular atrophy?

Yes — 14 recruiting clinical trials are currently listed for Autosomal dominant adult-onset proximal spinal muscular atrophy on UniteRare. See the clinical trials section on this page for phase, sponsor, and site details sourced from ClinicalTrials.gov.

Which specialists treat Autosomal dominant adult-onset proximal spinal muscular atrophy?

25 specialists and care centers treating Autosomal dominant adult-onset proximal spinal muscular atrophy are listed on UniteRare, sourced from ClinicalTrials.gov principal investigators, published research, and the NPPES NPI registry.