Activated PI3K-delta syndrome

Last reviewed

🖨 Print for my doctorAdvocacy Hub →
ORPHA:397596OMIM:615513D81.8
Who is this for?
Show terms as
1FDA treatments4Active trials15Specialists8Treatment centers1Financial resources

Where are you in your journey?

UniteRare data is sourced from FDA.gov, ClinicalTrials.gov, Orphanet, OMIM, and NORD.
Report missing data

Overview

Activated PI3K-delta syndrome (also called APDS, or sometimes PASLI disease) is a rare genetic disorder of the immune system. It is caused by mutations in genes that control a signaling protein called PI3K-delta, which plays a key role in how immune cells develop and function. When this protein is overactive, it disrupts the normal workings of the immune system, leading to a primary immunodeficiency. People with APDS typically experience frequent and severe infections, especially of the lungs, ears, and sinuses, often starting in early childhood. The condition can also cause the lymph nodes, spleen, and other lymphoid tissues to become enlarged (called lymphoproliferation). Over time, repeated lung infections can lead to permanent lung damage known as bronchiectasis. Some patients develop autoimmune problems, where the immune system mistakenly attacks the body's own cells, and there is also an increased risk of developing lymphoma, a type of blood cancer. There are two subtypes: APDS1, caused by mutations in the PIK3CD gene, and APDS2, caused by mutations in the PIK3R1 gene. Treatment has traditionally focused on managing infections with antibiotics and supporting the immune system with immunoglobulin replacement therapy. More recently, targeted therapies that directly inhibit the overactive PI3K-delta pathway have become available, including the FDA-approved drug leniolisib (Joenja), which represents a significant advance for patients with this condition. Hematopoietic stem cell transplant may also be considered in severe cases.

Also known as:

Key symptoms:

Frequent sinus infectionsFrequent ear infectionsRecurrent pneumonia or lung infectionsEnlarged lymph nodesEnlarged spleenPermanent lung damage (bronchiectasis)Frequent herpes virus infections (such as EBV or CMV)Low levels of antibodies in the bloodAutoimmune problems like low blood cell countsGrowth delay or short statureChronic diarrhea or digestive problemsIncreased risk of lymphoma (a type of blood cancer)Fatigue and low energyWarts or other viral skin infections

Clinical phenotype terms (24)— hover any for plain English
Recurrent upper and lower respiratory tract infectionsHP:0200117Increased circulating IgM levelHP:0003496Decreased total B cell countHP:0010976Chronic sinusitisHP:0011109Intestinal lymphoid nodular hyperplasiaHP:0011956Abnormal intestine morphologyHP:0002242Recurrent tonsillitisHP:0011110
Inheritance

Autosomal dominant

Passed on from just one parent; each child has about a 50% chance of inheriting it

Age of Onset

Childhood

Begins in childhood, roughly ages 1 to 12

Orphanet ↗OMIM ↗NORD ↗

FDA & Trial Timeline

7 events
Jun 2025New Biomarker-based Strategy to Screen and Monitor for Activated Phosphoinositide 3-kinase δ Syndrome

Assistance Publique - Hôpitaux de Paris

TrialRECRUITING
Aug 2023Pediatric Patients Aged 1 to 6 Years With APDS

Pharming Technologies B.V. — PHASE3

TrialACTIVE NOT RECRUITING
Mar 2023

Joenja: FDA approved

treatment of activated phosphoinositide 3-kinase delta (PI3K delta) syndrome (APDS) in adult and pediatric patients 12 years of age and older

FDAcompleted
Feb 2023Pediatric Patients Aged 4 to 11 Years With APDS

Pharming Technologies B.V. — PHASE3

TrialACTIVE NOT RECRUITING
May 2022Collecting Recorded Videos of Colonoscopy and Gastroscopy Tests for the Evaluation of the (ME-APDS).

Magentiq Eye LTD

TrialRECRUITING
Dec 2018Collecting Recorded Videos of Colonoscopy

Magentiq Eye LTD

TrialRECRUITING
Nov 2007Effect of Local Pamidronate in Preventing Bone Loss After Total Hip Arthroplasty

General and Teaching Hospital Celje — PHASE1

TrialNOT YET RECRUITING

Data sourced from FDA regulatory filings and ClinicalTrials.gov. Updated periodically.

Treatments

1 available

Joenja

leniolisib· Pharming Technologies B.V.Orphan Drug

treatment of activated phosphoinositide 3-kinase delta (PI3K delta) syndrome (APDS) in adult and pediatric patients 12 years of age and older

Clinical Trials

4 recruitingView all trials with filters →
Phase 32 trials
Pediatric Patients Aged 4 to 11 Years With APDS
Phase 3
Active
· Sites: Los Angeles, California; Standford, California +5 more · Age: 411 yrs
Pediatric Patients Aged 1 to 6 Years With APDS
Phase 3
Active
· Sites: Los Angeles, California; Bethesda, Maryland +7 more · Age: 16 yrs
Other2 trials
Collecting Recorded Videos of Colonoscopy and Gastroscopy Tests for the Evaluation of the (ME-APDS).
Actively Recruiting
PI: Haim Shirin, Prof. (Gastroenterology Department of Shamir Medical Cent) · Sites: Be’er Ya‘aqov · Age: 1899 yrs
New Biomarker-based Strategy to Screen and Monitor for Activated Phosphoinositide 3-kinase δ Syndrome
Actively Recruiting
PI: Sven Kracker, PHD (Institut National de la Santé Et de la Recherche M) · Sites: Bordeaux; Bordeaux +5 more · Age: 1299 yrs

Specialists

15 foundView all specialists →
SP
Sven Kracker, PHD
Specialist
PI on 1 active trial
VM
Virgil Dalm, MD
Specialist
PI on 1 active trial
AM
Anna Šedivá, MD
Specialist
PI on 1 active trial1 Activated PI3K-delta syndrome publication
KM
Koneti V Rao, MD
Specialist
PI on 1 active trial
JM
Joan C Marini, M.D.
BETHESDA, MD
Specialist
PI on 2 active trials
AM
Angela Dispenzieri, M.D.
ROCHESTER, MN
Specialist
PI on 5 active trials
JP
Jinqiao Sun, Ph.D.,M.D
Specialist
PI on 2 active trials
MM
Marco Pappagallo, MD
NEW YORK, NY
Specialist
PI on 4 active trials
AM
Athanasios Fassas, M.D.
Specialist
PI on 2 active trials
TZ
Timo Zondag
Specialist
2 Activated PI3K-delta syndrome publications
ZZ
Zijun Zhou
Specialist
2 Activated PI3K-delta syndrome publications
PH
P Martin van Hagen
Specialist
2 Activated PI3K-delta syndrome publications
ED
Elissa K Deenick
Specialist
2 Activated PI3K-delta syndrome publications
ST
Stuart G Tangye
Specialist
2 Activated PI3K-delta syndrome publications
MH
Maud Hermans
Specialist
2 Activated PI3K-delta syndrome publications

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Financial Resources

1 resources
Joenja(leniolisib)Pharming Technologies B.V.

Travel Grants

No travel grants are currently matched to Activated PI3K-delta syndrome.

Search all travel grants →NORD Financial Assistance ↗

Community

Open Activated PI3K-delta syndromeForum →

No community posts yet. Be the first to share your experience with Activated PI3K-delta syndrome.

Start the conversation →

Latest news about Activated PI3K-delta syndrome

Disease timeline:

New recruiting trial: Collecting Recorded Videos of Colonoscopy and Gastroscopy Tests for the Evaluation of the (ME-APDS).

A new clinical trial is recruiting patients for Activated PI3K-delta syndrome

New recruiting trial: Collecting Recorded Videos of Colonoscopy

A new clinical trial is recruiting patients for Activated PI3K-delta syndrome

New recruiting trial: New Biomarker-based Strategy to Screen and Monitor for Activated Phosphoinositide 3-kinase δ Syndrome

A new clinical trial is recruiting patients for Activated PI3K-delta syndrome

Caregiver Resources

NORD Caregiver Resources

Support, advocacy, and financial assistance for caregivers of rare disease patients.

Mental Health Support

Rare disease caregiving can be isolating. Connect with counseling and peer support.

Family & Caregiver Grants

Financial assistance programs specifically for caregivers of rare disease patients.

Social Security Disability

Learn how rare disease patients may qualify for SSDI/SSI benefits.

Questions for your doctor

Bring these to your next appointment

  • Q1.Which subtype of APDS does my child (or I) have, and what does that mean for treatment?,Is leniolisib (Joenja) appropriate for my case, and how do I access it?,How often will immunoglobulin replacement therapy be needed, and can it be done at home?,What signs of lymphoma should I watch for, and how often should screening be done?,Should my family members be tested for the same genetic mutation?,Is stem cell transplant something we should consider now or in the future?,What vaccines are safe, and which ones should be avoided?

Common questions about Activated PI3K-delta syndrome

What is Activated PI3K-delta syndrome?

Activated PI3K-delta syndrome (also called APDS, or sometimes PASLI disease) is a rare genetic disorder of the immune system. It is caused by mutations in genes that control a signaling protein called PI3K-delta, which plays a key role in how immune cells develop and function. When this protein is overactive, it disrupts the normal workings of the immune system, leading to a primary immunodeficiency. People with APDS typically experience frequent and severe infections, especially of the lungs, ears, and sinuses, often starting in early childhood. The condition can also cause the lymph nodes,

How is Activated PI3K-delta syndrome inherited?

Activated PI3K-delta syndrome follows a autosomal dominant inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Activated PI3K-delta syndrome typically begin?

Typical onset of Activated PI3K-delta syndrome is childhood. Age of onset can vary across affected individuals.

Are there clinical trials for Activated PI3K-delta syndrome?

Yes — 4 recruiting clinical trials are currently listed for Activated PI3K-delta syndrome on UniteRare. See the clinical trials section on this page for phase, sponsor, and site details sourced from ClinicalTrials.gov.

Which specialists treat Activated PI3K-delta syndrome?

15 specialists and care centers treating Activated PI3K-delta syndrome are listed on UniteRare, sourced from ClinicalTrials.gov principal investigators, published research, and the NPPES NPI registry.

What treatment and support options exist for Activated PI3K-delta syndrome?

1 patient support program are currently tracked on UniteRare for Activated PI3K-delta syndrome. See the treatments and support programs sections for copay assistance, eligibility, and contact details.