ISPD-related limb-girdle muscular dystrophy R20

Last reviewed

🖨 Print for my doctorAdvocacy Hub →
ORPHA:352479OMIM:616052G71.0
Who is this for?
Show terms as
8Treatment centers

Where are you in your journey?

UniteRare data is sourced from FDA.gov, ClinicalTrials.gov, Orphanet, OMIM, and NORD.
Report missing data

Overview

ISPD-related limb-girdle muscular dystrophy R20 (LGMD R20), also known as LGMD2U or muscular dystrophy-dystroglycanopathy type C7, is a rare inherited muscle disease caused by changes (mutations) in the ISPD gene (also called CRPPA). This gene plays an important role in a chemical process called glycosylation of a protein known as alpha-dystroglycan. When this protein is not properly modified, it cannot do its job of connecting muscle fibers to the surrounding tissue, which leads to progressive muscle weakness and damage. The disease primarily affects the muscles around the hips and shoulders (the limb-girdle muscles), making it harder over time to walk, climb stairs, lift objects, and perform everyday activities. Symptoms typically begin in childhood or adolescence, though the age of onset and severity can vary. Some patients may also experience elevated levels of creatine kinase (CK) in the blood, which is a marker of muscle damage. In some cases, the brain and eyes may also be mildly affected, though this is more common in the severe end of the spectrum of dystroglycanopathies. There is currently no cure for LGMD R20. Treatment focuses on managing symptoms and maintaining function for as long as possible. This includes physical therapy, occupational therapy, assistive devices, and monitoring for complications such as breathing difficulties or heart problems. Research into gene therapy and other disease-modifying treatments for dystroglycanopathies is ongoing, offering hope for future options.

Also known as:

Key symptoms:

Progressive weakness in hip and thigh musclesProgressive weakness in shoulder and upper arm musclesDifficulty walking and climbing stairsFrequent fallsDifficulty raising arms above the headWaddling gaitEnlarged calf muscles (pseudohypertrophy)Elevated creatine kinase (CK) levels in bloodDifficulty getting up from the floorFatigue during physical activityJoint stiffness or contracturesBreathing difficulties in advanced stagesPossible mild intellectual difficulties in some casesPossible mild eye abnormalities in some cases

Clinical phenotype terms (16)— hover any for plain English
Limb-girdle muscle weaknessHP:0003325Hypoglycosylation of alpha-dystroglycanHP:0030046Reduced vital capacityHP:0002792Calf muscle pseudohypertrophyHP:0003707Proximal upper limb muscle weaknessHP:0008997Highly elevated creatine kinaseHP:0030234Exercise-induced myoglobinuriaHP:0008305Abnormality of mental functionHP:0011446
Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Variable

Can begin at different ages, from infancy through adulthood

Orphanet ↗OMIM ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for ISPD-related limb-girdle muscular dystrophy R20.

View clinical trials →

No actively recruiting trials found for ISPD-related limb-girdle muscular dystrophy R20 at this time.

New trials open frequently. Follow this disease to get notified.

Search ClinicalTrials.gov ↗Join the ISPD-related limb-girdle muscular dystrophy R20 community →

No specialists are currently listed for ISPD-related limb-girdle muscular dystrophy R20.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to ISPD-related limb-girdle muscular dystrophy R20.

Search all travel grants →NORD Financial Assistance ↗

Community

Open ISPD-related limb-girdle muscular dystrophy R20Forum →

No community posts yet. Be the first to share your experience with ISPD-related limb-girdle muscular dystrophy R20.

Start the conversation →

Latest news about ISPD-related limb-girdle muscular dystrophy R20

No recent news articles for ISPD-related limb-girdle muscular dystrophy R20.

Follow this condition to be notified when news becomes available.

Caregiver Resources

NORD Caregiver Resources

Support, advocacy, and financial assistance for caregivers of rare disease patients.

Mental Health Support

Rare disease caregiving can be isolating. Connect with counseling and peer support.

Family & Caregiver Grants

Financial assistance programs specifically for caregivers of rare disease patients.

Social Security Disability

Learn how rare disease patients may qualify for SSDI/SSI benefits.

Questions for your doctor

Bring these to your next appointment

  • Q1.How quickly is the muscle weakness likely to progress in my case or my child's case?,How often should we have pulmonary function tests and heart evaluations?,What physical therapy program do you recommend, and how often should sessions occur?,Are there any clinical trials or experimental treatments available for ISPD-related dystroglycanopathy?,When should we consider using mobility aids like braces or a wheelchair?,Should other family members be tested for carrier status?,What signs or symptoms should prompt an urgent visit to the emergency room?

Common questions about ISPD-related limb-girdle muscular dystrophy R20

What is ISPD-related limb-girdle muscular dystrophy R20?

ISPD-related limb-girdle muscular dystrophy R20 (LGMD R20), also known as LGMD2U or muscular dystrophy-dystroglycanopathy type C7, is a rare inherited muscle disease caused by changes (mutations) in the ISPD gene (also called CRPPA). This gene plays an important role in a chemical process called glycosylation of a protein known as alpha-dystroglycan. When this protein is not properly modified, it cannot do its job of connecting muscle fibers to the surrounding tissue, which leads to progressive muscle weakness and damage. The disease primarily affects the muscles around the hips and shoulders

How is ISPD-related limb-girdle muscular dystrophy R20 inherited?

ISPD-related limb-girdle muscular dystrophy R20 follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.