Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome

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Overview

Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome, often called CHAPLE syndrome, is a very rare inherited disease that affects the immune system, blood vessels, and digestive tract all at once. The name describes the three main problems it causes: the immune system's complement pathway becomes overactive and attacks the body's own tissues, small blood vessels develop dangerous clots (a process called angiopathic thrombosis), and the intestines leak proteins into the gut instead of keeping them in the bloodstream (protein-losing enteropathy). The complement system is normally a helpful part of the immune system that fights infections. In CHAPLE syndrome, a missing or broken protein called CD55 means the complement system cannot be properly controlled. Without this brake, the immune system keeps firing and damages blood vessels and the lining of the intestines. This leads to swelling (edema), low protein levels in the blood, poor absorption of nutrients, and dangerous blood clots that can form in the intestines and other organs. Key symptoms include severe swelling, diarrhea, abdominal pain, weight loss, and life-threatening clots. The disease usually begins in childhood. Treatment has improved greatly with eculizumab, a drug that blocks the overactive complement system. With proper treatment, many patients see significant improvement in their symptoms and quality of life.

Also known as:

Key symptoms:

Severe swelling of the legs, abdomen, or face (edema)Chronic diarrheaAbdominal pain and crampingUnintended weight loss and poor growthLow protein levels in the blood (hypoproteinemia)Blood clots in the intestines or other organs (thrombosis)Fatigue and general weaknessNausea and vomitingMalnutrition and vitamin deficienciesRecurrent infections due to immune system problemsFluid buildup in the abdomen (ascites)Anemia (low red blood cell count)

Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Childhood

Begins in childhood, roughly ages 1 to 12

Orphanet ↗OMIM ↗NORD ↗

FDA & Trial Timeline

1 event
Mar 2026A Study to Test the Safety of Pozelimab in Pediatric Participants 1 to 5 Years of Age With a Rare Disease Called CHAPLE (Complement Hyperactivation, Angiopathic Thrombosis, Protein-losing Enteropathy) Disease

Regeneron Pharmaceuticals — PHASE4

TrialRECRUITING

Data sourced from FDA regulatory filings and ClinicalTrials.gov. Updated periodically.

Treatments

1 available

Veopoz

pozelimab-bbfg· Regeneron Pharmaceuticals, Inc.■ Boxed WarningOrphan Drug
Treatment of patients 1 year of age and older with CD55 deficiency with hyperactivation of complement, angiopathic thrombosis, and protein-losing enteropathy (CHAPLE disease). First approved treatment

Treatment of patients 1 year of age and older with CD55 deficiency with hyperactivation of complement, angiopathic thrombosis, and protein-losing enteropathy (CHAPLE disease). First approved treatment for CHAPLE disease.

Clinical Trials

1 recruitingView all trials with filters →
Phase 41 trial
A Study to Test the Safety of Pozelimab in Pediatric Participants 1 to 5 Years of Age With a Rare Disease Called CHAPLE (Complement Hyperactivation, Angiopathic Thrombosis, Protein-losing Enteropathy) Disease
Phase 4
Actively Recruiting
PI: Clinical Trial Management (Regeneron Pharmaceuticals) · Sites: Istanbul · Age: 15 yrs

No specialists are currently listed for Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Financial Resources

1 resources

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Travel Grants

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Latest news about Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome

Disease timeline:

New recruiting trial: A Study to Test the Safety of Pozelimab in Pediatric Participants 1 to 5 Years of Age With a Rare Disease Called CHAPLE (Complement Hyperactivation, Angiopathic Thrombosis, Protein-losing Enteropathy) Disease

A new clinical trial is recruiting patients for Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome

Caregiver Resources

NORD Caregiver Resources

Support, advocacy, and financial assistance for caregivers of rare disease patients.

Mental Health Support

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Family & Caregiver Grants

Financial assistance programs specifically for caregivers of rare disease patients.

Social Security Disability

Learn how rare disease patients may qualify for SSDI/SSI benefits.

Questions for your doctor

Bring these to your next appointment

  • Q1.Is genetic testing available for my whole family to see if others are carriers or affected?,Am I or my child a good candidate for eculizumab, and how do we access it?,What vaccinations are needed before starting complement-blocking treatment?,How often will monitoring blood tests and infusions be needed?,What are the warning signs of a blood clot and when should we go to the emergency room?,Are there any clinical trials or research studies we could join?,What dietary changes or nutritional support are recommended?

Common questions about Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome

What is Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome?

Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome, often called CHAPLE syndrome, is a very rare inherited disease that affects the immune system, blood vessels, and digestive tract all at once. The name describes the three main problems it causes: the immune system's complement pathway becomes overactive and attacks the body's own tissues, small blood vessels develop dangerous clots (a process called angiopathic thrombosis), and the intestines leak proteins into the gut instead of keeping them in the bloodstream (protein-losing enteropathy). The complement

How is Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome inherited?

Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome typically begin?

Typical onset of Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome is childhood. Age of onset can vary across affected individuals.

Are there clinical trials for Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome?

Yes — 1 recruiting clinical trial is currently listed for Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome on UniteRare. See the clinical trials section on this page for phase, sponsor, and site details sourced from ClinicalTrials.gov.

What treatment and support options exist for Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome?

1 patient support program are currently tracked on UniteRare for Complement hyperactivation-angiopathic thrombosis-protein-losing enteropathy syndrome. See the treatments and support programs sections for copay assistance, eligibility, and contact details.