Temtamy preaxial brachydactyly syndrome

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ORPHA:363417OMIM:605282Q87.2
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Overview

Temtamy preaxial brachydactyly syndrome is an extremely rare genetic condition that primarily affects the development of the hands, feet, and brain. It was first described by Professor Samia Temtamy. The term 'preaxial brachydactyly' refers to shortening of the fingers and toes on the thumb side (the preaxial side) of the hands and feet. People with this condition typically have shortened fingers and toes, particularly affecting the thumbs and big toes, along with other skeletal differences in the hands and feet. Beyond the limb findings, this syndrome can also affect brain development. Many individuals experience intellectual disability, which can range from mild to moderate. Some patients may also have seizures, hearing loss, and distinctive facial features. Eye abnormalities, including problems with the retina or optic nerve, have also been reported in some cases. Because this condition is so rare, there is no specific cure or targeted treatment available. Management focuses on addressing individual symptoms. This may include surgery or occupational therapy for hand and foot differences, special education support for learning difficulties, anti-seizure medications if epilepsy is present, and hearing aids if hearing loss occurs. A team of specialists working together provides the best care for affected individuals. Early intervention services for children can help maximize developmental potential.

Key symptoms:

Shortened fingers, especially the thumbsShortened toes, especially the big toesIntellectual disabilitySeizures or epilepsyHearing lossDistinctive facial featuresEye or vision problemsDelayed developmental milestonesAbnormal bone structure in the hands and feetLow muscle toneSpeech and language delaysGrowth delays

Clinical phenotype terms (48)— hover any for plain English
Duplication of thumb phalanxHP:0009942Abnormal digit morphologyHP:0011297Abnormally large globeHP:0001090Widely-spaced maxillary central incisorsHP:0001566Proximal finger symphalangismHP:0006152Severe sensorineural hearing impairmentHP:0008625Complete duplication of proximal phalanx of the thumbHP:0009608Partial duplication of thumb phalanxHP:0009944Complete duplication of the middle phalanx of the 3rd fingerHP:0009966Partial duplication of the proximal phalanx of the 3rd fingerHP:0009970Talon cuspHP:0011087Synostosis of carpals/tarsalsHP:0100266
Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Neonatal

Begins at or shortly after birth (first 4 weeks)

Orphanet ↗OMIM ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for Temtamy preaxial brachydactyly syndrome.

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No actively recruiting trials found for Temtamy preaxial brachydactyly syndrome at this time.

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No specialists are currently listed for Temtamy preaxial brachydactyly syndrome.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to Temtamy preaxial brachydactyly syndrome.

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Community

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Caregiver Resources

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Social Security Disability

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Questions for your doctor

Bring these to your next appointment

  • Q1.What specific CHSY1 gene changes were found, and what do they mean for my child?,What developmental milestones should I watch for, and when should I be concerned?,Does my child need seizure medication, and what are the side effects?,What therapies (occupational, speech, physical) would benefit my child most right now?,How often should hearing and vision be tested?,Are there any surgical options to improve hand or foot function?,What is the chance of having another child with this condition, and should other family members be tested?

Common questions about Temtamy preaxial brachydactyly syndrome

What is Temtamy preaxial brachydactyly syndrome?

Temtamy preaxial brachydactyly syndrome is an extremely rare genetic condition that primarily affects the development of the hands, feet, and brain. It was first described by Professor Samia Temtamy. The term 'preaxial brachydactyly' refers to shortening of the fingers and toes on the thumb side (the preaxial side) of the hands and feet. People with this condition typically have shortened fingers and toes, particularly affecting the thumbs and big toes, along with other skeletal differences in the hands and feet. Beyond the limb findings, this syndrome can also affect brain development. Many

How is Temtamy preaxial brachydactyly syndrome inherited?

Temtamy preaxial brachydactyly syndrome follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Temtamy preaxial brachydactyly syndrome typically begin?

Typical onset of Temtamy preaxial brachydactyly syndrome is neonatal. Age of onset can vary across affected individuals.