MYO5B-related progressive familial intrahepatic cholestasis

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ORPHA:480491OMIM:619868K76.8
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Overview

MYO5B-related progressive familial intrahepatic cholestasis (also called PFIC type 6 or MYO5B-PFIC) is a rare inherited liver disease caused by changes in the MYO5B gene. This gene provides instructions for making a protein called myosin Vb, which helps move important proteins to the right places inside liver cells. When myosin Vb does not work properly, bile — a digestive fluid made by the liver — cannot flow out of liver cells normally. Bile then builds up inside the liver, causing damage over time. This condition belongs to a group of diseases called progressive familial intrahepatic cholestasis (PFIC). The disease usually appears in infancy or early childhood. The most noticeable symptom is intense, persistent itching caused by bile acids building up in the blood. Children may also develop yellowing of the skin and eyes (jaundice), poor growth, and liver scarring (cirrhosis) if untreated. Some children with MYO5B mutations also have a gut condition called microvillus inclusion disease (MVID), which causes severe watery diarrhea from birth. Treatment options include medications to improve bile flow, surgical procedures to divert bile away from the liver, and in severe cases, liver transplantation. Newer targeted medications are being studied and some have shown promise. Early diagnosis and treatment are important to slow liver damage and improve quality of life.

Also known as:

Key symptoms:

Severe, persistent itching all over the bodyYellowing of the skin and whites of the eyes (jaundice)Poor weight gain and slow growth in infants and childrenEnlarged liver and spleenPale or clay-colored stoolsDark urineFatigue and low energyLiver scarring (cirrhosis) over timeElevated liver enzymes on blood testsFat-soluble vitamin deficiencies (vitamins A, D, E, K)Bone thinning due to vitamin D and calcium problemsIn some cases, severe watery diarrhea from birth (if microvillus inclusion disease is also present)

Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Infantile

Begins in infancy, roughly 1 month to 2 years old

Orphanet ↗OMIM ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for MYO5B-related progressive familial intrahepatic cholestasis.

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No actively recruiting trials found for MYO5B-related progressive familial intrahepatic cholestasis at this time.

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No specialists are currently listed for MYO5B-related progressive familial intrahepatic cholestasis.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to MYO5B-related progressive familial intrahepatic cholestasis.

Search all travel grants →NORD Financial Assistance ↗

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Caregiver Resources

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Questions for your doctor

Bring these to your next appointment

  • Q1.What stage is my child's liver disease at right now, and how quickly might it progress?,Which treatments are most appropriate for my child's specific MYO5B mutation and symptoms?,Should we consider surgical bile diversion, and what are the risks and benefits?,At what point would you recommend evaluation for liver transplantation?,Does my child need to be tested for microvillus inclusion disease as well?,What vitamins and nutritional supplements does my child need, and how do we monitor them?,Are there any clinical trials for MYO5B-related PFIC that my child might be eligible for?

Common questions about MYO5B-related progressive familial intrahepatic cholestasis

What is MYO5B-related progressive familial intrahepatic cholestasis?

MYO5B-related progressive familial intrahepatic cholestasis (also called PFIC type 6 or MYO5B-PFIC) is a rare inherited liver disease caused by changes in the MYO5B gene. This gene provides instructions for making a protein called myosin Vb, which helps move important proteins to the right places inside liver cells. When myosin Vb does not work properly, bile — a digestive fluid made by the liver — cannot flow out of liver cells normally. Bile then builds up inside the liver, causing damage over time. This condition belongs to a group of diseases called progressive familial intrahepatic choles

How is MYO5B-related progressive familial intrahepatic cholestasis inherited?

MYO5B-related progressive familial intrahepatic cholestasis follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does MYO5B-related progressive familial intrahepatic cholestasis typically begin?

Typical onset of MYO5B-related progressive familial intrahepatic cholestasis is infantile. Age of onset can vary across affected individuals.