Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency

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ORPHA:319563OMIM:616126D84.8
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Overview

Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency is an extremely rare inherited immune disorder. It is caused by the complete lack of a protein called ISG15 (interferon-stimulated gene 15), which plays an important role in helping the body fight off certain infections, particularly mycobacteria. Mycobacteria are a family of germs that include the bacteria causing tuberculosis (TB) and a group of related organisms called non-tuberculous mycobacteria (NTM), as well as the BCG vaccine strain. People with this condition are unusually vulnerable to infections caused by mycobacteria, including severe reactions to the BCG vaccine, which is routinely given in many countries to prevent tuberculosis. The disease typically appears in early childhood, often after BCG vaccination, and can cause widespread or life-threatening mycobacterial infections. Interestingly, patients with complete ISG15 deficiency also show features related to abnormal interferon signaling, which can lead to brain calcifications and sometimes seizures, resembling a condition called Aicardi-Goutières syndrome. Treatment focuses on aggressive antibiotic therapy to control mycobacterial infections and, in some cases, interferon-gamma supplementation to boost the immune response. Avoiding BCG vaccination is critical for known carriers and affected individuals. Early diagnosis through genetic testing can be life-saving, as it allows doctors to take preventive measures and start treatment promptly.

Also known as:

Key symptoms:

Severe reaction to BCG vaccinationRecurrent or widespread mycobacterial infectionsProlonged feversSwollen lymph nodesSkin lesions or abscesses from mycobacterial infectionBrain calcifications (calcium deposits in the brain)SeizuresFailure to thrive or poor weight gain in infancyBone infections caused by mycobacteriaLung infectionsFatigue and general weaknessEnlarged liver or spleen

Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Infantile

Begins in infancy, roughly 1 month to 2 years old

Orphanet ↗OMIM ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency.

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No actively recruiting trials found for Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency at this time.

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No specialists are currently listed for Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency.

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Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency.

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Community

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Questions for your doctor

Bring these to your next appointment

  • Q1.Should my child avoid any vaccines besides BCG?,How long will my child need to take antibiotics, and what side effects should I watch for?,Is interferon-gamma therapy appropriate for my child, and how do we access it?,What neurological monitoring does my child need, and how often?,Should other family members be genetically tested?,Are there any clinical trials or new treatments being studied for this condition?,What emergency signs should prompt me to go to the hospital immediately?

Common questions about Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency

What is Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency?

Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency is an extremely rare inherited immune disorder. It is caused by the complete lack of a protein called ISG15 (interferon-stimulated gene 15), which plays an important role in helping the body fight off certain infections, particularly mycobacteria. Mycobacteria are a family of germs that include the bacteria causing tuberculosis (TB) and a group of related organisms called non-tuberculous mycobacteria (NTM), as well as the BCG vaccine strain. People with this condition are unusually vulnerable to infections cau

How is Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency inherited?

Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency typically begin?

Typical onset of Mendelian susceptibility to mycobacterial diseases due to complete ISG15 deficiency is infantile. Age of onset can vary across affected individuals.