KLHL9-related early-onset distal myopathy

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Overview

KLHL9-related early-onset distal myopathy is an extremely rare inherited muscle disease caused by a change (mutation) in the KLHL9 gene. This condition primarily affects the muscles farthest from the center of the body, especially those in the lower legs and feet. It typically begins in childhood or adolescence, which is earlier than most other distal myopathies. The disease gets its name from the pattern of muscle weakness it causes — 'distal' means the muscles at the ends of the limbs are affected first, rather than those closer to the trunk. People with this condition usually first notice difficulty walking, foot drop (trouble lifting the front part of the foot), and weakness in the lower legs. Over time, the weakness may slowly progress, but it tends to remain mostly in the distal muscles. The upper limbs may also become mildly affected later in the disease course. Unlike some other muscular dystrophies, the heart and breathing muscles are generally not significantly involved. There is currently no cure or disease-modifying treatment for KLHL9-related distal myopathy. Management focuses on supportive care, including physical therapy, orthotic devices such as ankle-foot braces to help with walking, and regular monitoring by a neuromuscular specialist. Because this condition is so rare, much of what is known comes from a very small number of reported families, and research is ongoing to better understand the disease and develop potential therapies.

Key symptoms:

Weakness in the lower legs and feetFoot drop (difficulty lifting the front of the foot)Difficulty walking or runningTripping or stumbling frequentlyMuscle wasting in the lower legsHigh-arched feet (pes cavus)Difficulty with activities requiring fine foot movementsMild weakness in the hands or forearms in later stagesSlowly progressive muscle weaknessAbnormal walking pattern (gait changes)

Clinical phenotype terms (17)— hover any for plain English
Ankle flexion contractureHP:0006466Weakness of the intrinsic hand musclesHP:0009005Progressive distal muscle weaknessHP:0009063Abnormal calf musculature morphologyHP:0001430Steppage gaitHP:0003376Absent patellar reflexesHP:0006844Impaired distal tactile sensationHP:0006937Intrinsic hand muscle atrophyHP:0008954Amyotrophy of ankle musculatureHP:0009031Abnormal circulating creatine kinase concentrationHP:0040081
Inheritance

Autosomal dominant

Passed on from just one parent; each child has about a 50% chance of inheriting it

Age of Onset

Juvenile

Begins in the teen years

Orphanet ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for KLHL9-related early-onset distal myopathy.

View clinical trials →

No actively recruiting trials found for KLHL9-related early-onset distal myopathy at this time.

New trials open frequently. Follow this disease to get notified.

Search ClinicalTrials.gov ↗Join the KLHL9-related early-onset distal myopathy community →

No specialists are currently listed for KLHL9-related early-onset distal myopathy.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to KLHL9-related early-onset distal myopathy.

Search all travel grants →NORD Financial Assistance ↗

Community

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Caregiver Resources

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Social Security Disability

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Questions for your doctor

Bring these to your next appointment

  • Q1.How quickly is this condition likely to progress in my case?,Would ankle-foot orthoses or other bracing help me walk more safely?,What types of physical activity are safe and beneficial for me?,Should my family members be tested for the KLHL9 gene change?,Are there any clinical trials or research studies I could participate in?,How often should I have follow-up appointments to monitor my muscle strength?,What should I watch for that would indicate the disease is getting worse?

Common questions about KLHL9-related early-onset distal myopathy

What is KLHL9-related early-onset distal myopathy?

KLHL9-related early-onset distal myopathy is an extremely rare inherited muscle disease caused by a change (mutation) in the KLHL9 gene. This condition primarily affects the muscles farthest from the center of the body, especially those in the lower legs and feet. It typically begins in childhood or adolescence, which is earlier than most other distal myopathies. The disease gets its name from the pattern of muscle weakness it causes — 'distal' means the muscles at the ends of the limbs are affected first, rather than those closer to the trunk. People with this condition usually first notice

How is KLHL9-related early-onset distal myopathy inherited?

KLHL9-related early-onset distal myopathy follows a autosomal dominant inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does KLHL9-related early-onset distal myopathy typically begin?

Typical onset of KLHL9-related early-onset distal myopathy is juvenile. Age of onset can vary across affected individuals.