Keratinopathic ichthyosis

Last reviewed

🖨 Print for my doctorAdvocacy Hub →
ORPHA:281103
Who is this for?
Show terms as
6Specialists8Treatment centers

Where are you in your journey?

UniteRare data is sourced from FDA.gov, ClinicalTrials.gov, Orphanet, OMIM, and NORD.
Report missing data

Overview

Keratinopathic ichthyosis is a group of rare inherited skin disorders caused by mutations in genes that produce keratin, a key protein that gives skin its strength and structure. The condition was previously known by names such as epidermolytic ichthyosis (EI), epidermolytic hyperkeratosis, and bullous congenital ichthyosiform erythroderma (bullous CIE). It affects the outermost layer of the skin, causing it to become abnormally thick, scaly, and fragile. Babies with keratinopathic ichthyosis are often born with red, fragile skin that blisters easily. As children grow older, the blistering tends to decrease, but the skin becomes increasingly thick and scaly, especially over joints and skin folds. The thickened skin can have a ridged or corrugated appearance. A distinctive and sometimes distressing feature is a strong body odor caused by bacteria growing in the moist, thickened skin folds. The severity of the condition varies widely, even among members of the same family. There is currently no cure for keratinopathic ichthyosis. Treatment focuses on managing symptoms and improving quality of life. This includes regular moisturizing, gentle removal of excess scale, preventing and treating skin infections, and managing odor. Retinoid medications may be used in more severe cases to help reduce skin thickening. Ongoing research into gene therapy and other targeted treatments offers hope for future options.

Also known as:

Key symptoms:

Thick, scaly skin covering large areas of the bodySkin blistering, especially in newborns and young childrenRedness of the skin at birthRidged or corrugated thickened skin, particularly over jointsStrong body odor from bacterial growth in skin foldsSkin peeling or sheddingSkin infections that keep coming backPain or tenderness of the skinDifficulty with movement due to tight, thickened skin over jointsHeat intolerance due to impaired sweatingItchingThickened skin on palms of hands and soles of feetFragile skin that tears or breaks easily

Inheritance

Autosomal dominant

Passed on from just one parent; each child has about a 50% chance of inheriting it

Age of Onset

Neonatal

Begins at or shortly after birth (first 4 weeks)

Orphanet ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for Keratinopathic ichthyosis.

View clinical trials →

No actively recruiting trials found for Keratinopathic ichthyosis at this time.

New trials open frequently. Follow this disease to get notified.

Search ClinicalTrials.gov ↗Join the Keratinopathic ichthyosis community →

Specialists

6 foundView all specialists →
ZY
Zhou Yang
Specialist
1 Keratinopathic ichthyosis publication
ZX
Zhe Xu
Specialist
1 Keratinopathic ichthyosis publication
XX
Xin Xiang
SALEM, OR
Specialist
1 Keratinopathic ichthyosis publication
BZ
Bin Zhang
Specialist
1 Keratinopathic ichthyosis publication
LM
Lin Ma
Specialist
1 Keratinopathic ichthyosis publication
RH
Rui He
FALLS CHURCH, VA
Specialist
1 Keratinopathic ichthyosis publication

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to Keratinopathic ichthyosis.

Search all travel grants →NORD Financial Assistance ↗

Community

Open Keratinopathic ichthyosisForum →

No community posts yet. Be the first to share your experience with Keratinopathic ichthyosis.

Start the conversation →

Latest news about Keratinopathic ichthyosis

No recent news articles for Keratinopathic ichthyosis.

Follow this condition to be notified when news becomes available.

Caregiver Resources

NORD Caregiver Resources

Support, advocacy, and financial assistance for caregivers of rare disease patients.

Mental Health Support

Rare disease caregiving can be isolating. Connect with counseling and peer support.

Family & Caregiver Grants

Financial assistance programs specifically for caregivers of rare disease patients.

Social Security Disability

Learn how rare disease patients may qualify for SSDI/SSI benefits.

Questions for your doctor

Bring these to your next appointment

  • Q1.What specific gene mutation is causing my (or my child's) keratinopathic ichthyosis, and does this affect the expected severity?,What daily skin care routine do you recommend, and which specific products work best?,How can we best manage the body odor associated with this condition?,When should I be concerned about a skin infection, and what should I do?,Would oral retinoids be appropriate, and what are the risks and benefits?,Are there any clinical trials or new treatments being studied that we could consider?,What is the chance of passing this condition to future children, and is genetic counseling available?

Common questions about Keratinopathic ichthyosis

What is Keratinopathic ichthyosis?

Keratinopathic ichthyosis is a group of rare inherited skin disorders caused by mutations in genes that produce keratin, a key protein that gives skin its strength and structure. The condition was previously known by names such as epidermolytic ichthyosis (EI), epidermolytic hyperkeratosis, and bullous congenital ichthyosiform erythroderma (bullous CIE). It affects the outermost layer of the skin, causing it to become abnormally thick, scaly, and fragile. Babies with keratinopathic ichthyosis are often born with red, fragile skin that blisters easily. As children grow older, the blistering te

How is Keratinopathic ichthyosis inherited?

Keratinopathic ichthyosis follows a autosomal dominant inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Keratinopathic ichthyosis typically begin?

Typical onset of Keratinopathic ichthyosis is neonatal. Age of onset can vary across affected individuals.

Which specialists treat Keratinopathic ichthyosis?

6 specialists and care centers treating Keratinopathic ichthyosis are listed on UniteRare, sourced from ClinicalTrials.gov principal investigators, published research, and the NPPES NPI registry.