Hereditary benign intraepithelial dyskeratosis

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ORPHA:352657OMIM:127600Q82.8
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Overview

Hereditary benign intraepithelial dyskeratosis (HBID), also known as Witkop disease or Witkop-Von Sallmann syndrome, is a rare genetic condition that affects the surface tissues (epithelium) of the eyes and mouth. People with this condition develop raised, white or grayish plaques on the inner lining of the mouth (oral mucosa) and on the surface of the eyes (conjunctiva and cornea). The eye involvement can cause redness, irritation, tearing, and a feeling of grittiness, and in some cases the growths on the eye surface can affect vision. The mouth plaques are usually painless and appear on the gums, inner cheeks, tongue, and floor of the mouth. These changes are typically present from early childhood and persist throughout life. Despite the word 'dyskeratosis' in the name, this condition is considered benign, meaning it does not turn into cancer. The abnormal tissue growths result from a problem in how the surface skin cells mature and shed. Treatment is mainly focused on managing symptoms. Eye drops, lubricants, and sometimes surgical removal of eye plaques may be needed to protect vision and relieve discomfort. The oral plaques usually do not require treatment unless they cause problems. Regular monitoring by eye and dental specialists is important to manage the condition over time.

Also known as:

Key symptoms:

White or grayish raised patches on the inside of the mouthWhite or grayish growths on the surface of the eyeRed, irritated eyesExcessive tearing of the eyesGritty or foreign body sensation in the eyesBlurred vision if eye growths affect the corneaThickened tissue on the gums, cheeks, or tongueLight sensitivityEye inflammation that comes and goesPainless white plaques in the mouth

Inheritance

Autosomal dominant

Passed on from just one parent; each child has about a 50% chance of inheriting it

Age of Onset

Childhood

Begins in childhood, roughly ages 1 to 12

Orphanet ↗OMIM ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for Hereditary benign intraepithelial dyskeratosis.

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No actively recruiting trials found for Hereditary benign intraepithelial dyskeratosis at this time.

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No specialists are currently listed for Hereditary benign intraepithelial dyskeratosis.

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Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to Hereditary benign intraepithelial dyskeratosis.

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Community

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Caregiver Resources

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Social Security Disability

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Questions for your doctor

Bring these to your next appointment

  • Q1.How often should my eyes (or my child's eyes) be checked for new growths?,What signs should I watch for that would mean the eye plaques need to be removed?,Are there eye drops or treatments that can slow the growth of the plaques?,If surgery is needed to remove eye plaques, how likely are they to come back?,Should other family members be examined for this condition?,Is genetic testing recommended for our family, and what would it involve?,Are there any activities or environmental factors I should avoid to protect my eyes?

Common questions about Hereditary benign intraepithelial dyskeratosis

What is Hereditary benign intraepithelial dyskeratosis?

Hereditary benign intraepithelial dyskeratosis (HBID), also known as Witkop disease or Witkop-Von Sallmann syndrome, is a rare genetic condition that affects the surface tissues (epithelium) of the eyes and mouth. People with this condition develop raised, white or grayish plaques on the inner lining of the mouth (oral mucosa) and on the surface of the eyes (conjunctiva and cornea). The eye involvement can cause redness, irritation, tearing, and a feeling of grittiness, and in some cases the growths on the eye surface can affect vision. The mouth plaques are usually painless and appear on the

How is Hereditary benign intraepithelial dyskeratosis inherited?

Hereditary benign intraepithelial dyskeratosis follows a autosomal dominant inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Hereditary benign intraepithelial dyskeratosis typically begin?

Typical onset of Hereditary benign intraepithelial dyskeratosis is childhood. Age of onset can vary across affected individuals.