CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

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ORPHA:566067OMIM:260570D89.8
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2Specialists8Treatment centers

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UniteRare data is sourced from FDA.gov, ClinicalTrials.gov, Orphanet, OMIM, and NORD.
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Overview

CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome is a very rare inherited disease caused by changes (mutations) in the CEBPE gene. This gene gives instructions for making a protein called C/EBP epsilon, which is essential for the normal development and function of neutrophils — the white blood cells that are your body's first line of defense against bacterial and fungal infections. When this protein does not work properly, neutrophils fail to mature correctly and cannot fight infections effectively. At the same time, the immune system becomes overactive in other ways, causing episodes of inflammation even without an obvious infection. People with this condition typically experience a combination of three main problems: frequent and severe infections (immunodeficiency), episodes of unexplained fever and inflammation (autoinflammation), and poorly functioning neutrophils (neutrophil dysfunction). Common symptoms include recurrent skin infections, lung infections, swollen lymph nodes, and periodic fevers. Some patients also develop inflammatory skin rashes or bowel problems. This condition is sometimes referred to by the abbreviation AAINS. It overlaps in some ways with Specific Granule Deficiency (SGD), which is also caused by CEBPE mutations. Treatment focuses on preventing and treating infections, and managing inflammation. Stem cell transplant has been used in severe cases and may offer the best chance of long-term improvement.

Also known as:

Key symptoms:

Frequent and severe bacterial infectionsRecurring skin infections, abscesses, or boilsRepeated lung infections or pneumoniaPeriodic unexplained feversSwollen lymph nodesPoor wound healingInflammatory skin rashesBowel inflammation or diarrheaAbnormal or absent granules in neutrophils seen on blood testsElevated inflammatory markers in the blood during flares

Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Infantile

Begins in infancy, roughly 1 month to 2 years old

Orphanet ↗OMIM ↗NORD ↗

FDA & Trial Timeline

8 events
Sep 2024Blinatumomab for CNI-Resistant/Intolerant SRNS in Children

The Children's Hospital of Zhejiang University School of Medicine — PHASE1

TrialRECRUITING
Aug 2024Mycophenolate-Based Therapy for Kidney Transplant Recipients Without HLA-DQ Mismatch

University Hospital, Antwerp — PHASE4

TrialRECRUITING
Jun 2024Botox Versus Tacrolimus in Psoriasis Vulgaris

Assiut University — PHASE4

TrialNOT YET RECRUITING
Mar 2024Safety, Tolerability, and Efficacy of Immunomodulation With A Monoclonal Antibody Against CD40L in Combination With Transplanted Islet Cells in Adults With Brittle Type 1 Diabetes Mellitus (T1D)

University of Chicago — PHASE1, PHASE2

TrialRECRUITING
Dec 2023Assessment of Biomarker-Guided CNI Substitution In Kidney Transplantation

National Institute of Allergy and Infectious Diseases (NIAID) — PHASE2

TrialRECRUITING
Nov 2022The Lowest Effective Dose of Post-Transplantation Cyclophosphamide in Combination With Sirolimus and Mycophenolate Mofetil as Graft-Versus-Host Disease Prophylaxis After Reduced Intensity Conditioning and Peripheral Blood Stem Cell Transplantation

National Cancer Institute (NCI) — PHASE1, PHASE2

TrialRECRUITING
Jul 2022Calcineurin Inhibitor in NEuRoloGically Deceased Donors to Decrease Kidney delaYed Graft Function (CINERGY)

Université de Sherbrooke — PHASE2

TrialACTIVE NOT RECRUITING
Jul 2021A Study to Evaluate the Benefits and Risks of Conversion of Existing Adolescent Kidney Transplant Recipients Aged 12 to <18 Years to a Belatacept-based Immunosuppressive Regimen as Compared to Continuation of a Calcineurin Inhibitor-based Regimen, and Their Adherence to Immunosuppressive Medications

Bristol-Myers Squibb — PHASE3

TrialRECRUITING

Data sourced from FDA regulatory filings and ClinicalTrials.gov. Updated periodically.

Treatments

No FDA-approved treatments are currently listed for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome.

View clinical trials →

No actively recruiting trials found for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome at this time.

New trials open frequently. Follow this disease to get notified.

Search ClinicalTrials.gov ↗Join the CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome community →

Specialists

2 foundView all specialists →
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Specialist
PI on 28 active trials

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome.

Search all travel grants →NORD Financial Assistance ↗

Community

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Latest news about CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

Disease timeline:

New recruiting trial: Mycophenolate-Based Therapy for Kidney Transplant Recipients Without HLA-DQ Mismatch

A new clinical trial is recruiting patients for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

New recruiting trial: A Study to Evaluate the Benefits and Risks of Conversion of Existing Adolescent Kidney Transplant Recipients Aged 12 to <18 Years to a Belatacept-based Immunosuppressive Regimen as Compared to Continuation of a Calcineurin Inhibitor-based Regimen, and Their Adherence to Immunosuppressive Medications

A new clinical trial is recruiting patients for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

New recruiting trial: The Lowest Effective Dose of Post-Transplantation Cyclophosphamide in Combination With Sirolimus and Mycophenolate Mofetil as Graft-Versus-Host Disease Prophylaxis After Reduced Intensity Conditioning and Peripheral Blood Stem Cell Transplantation

A new clinical trial is recruiting patients for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

New recruiting trial: Safety, Tolerability, and Efficacy of Immunomodulation With A Monoclonal Antibody Against CD40L in Combination With Transplanted Islet Cells in Adults With Brittle Type 1 Diabetes Mellitus (T1D)

A new clinical trial is recruiting patients for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

New recruiting trial: Blinatumomab for CNI-Resistant/Intolerant SRNS in Children

A new clinical trial is recruiting patients for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

New recruiting trial: Assessment of Biomarker-Guided CNI Substitution In Kidney Transplantation

A new clinical trial is recruiting patients for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

New recruiting trial: Early Use of Long-acting Tacrolimus in Lung Transplant Recipients

A new clinical trial is recruiting patients for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

New recruiting trial: A Study to Evaluate Efficacy, Safety, and Tolerability of Povetacicept in Participants With Primary Membranous Nephropathy (pMN)

A new clinical trial is recruiting patients for CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

Caregiver Resources

NORD Caregiver Resources

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Mental Health Support

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Family & Caregiver Grants

Financial assistance programs specifically for caregivers of rare disease patients.

Social Security Disability

Learn how rare disease patients may qualify for SSDI/SSI benefits.

Questions for your doctor

Bring these to your next appointment

  • Q1.What preventive medications should my child take every day, and what are the possible side effects?,What signs of infection should prompt me to go to the emergency room immediately?,Is my child a candidate for stem cell transplantation, and what would that process involve?,Are there any vaccines that are not safe for my child because of this condition?,Should other family members be tested for the CEBPE gene mutation?,Are there any clinical trials or research studies we could participate in?,What specialists should be part of my child's care team, and how often should we see each one?

Common questions about CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome

What is CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome?

CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome is a very rare inherited disease caused by changes (mutations) in the CEBPE gene. This gene gives instructions for making a protein called C/EBP epsilon, which is essential for the normal development and function of neutrophils — the white blood cells that are your body's first line of defense against bacterial and fungal infections. When this protein does not work properly, neutrophils fail to mature correctly and cannot fight infections effectively. At the same time, the immune system becomes overactive in oth

How is CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome inherited?

CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome typically begin?

Typical onset of CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome is infantile. Age of onset can vary across affected individuals.

Which specialists treat CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome?

2 specialists and care centers treating CEBPE-associated autoinflammation-immunodeficiency-neutrophil dysfunction syndrome are listed on UniteRare, sourced from ClinicalTrials.gov principal investigators, published research, and the NPPES NPI registry.