Autosomal recessive spastic paraplegia type 56

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ORPHA:320411OMIM:615030G11.4
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Overview

Autosomal recessive spastic paraplegia type 56 (SPG56) is a rare inherited neurological condition that primarily affects the nervous system, causing progressive stiffness and weakness in the legs. It is also known as hereditary spastic paraplegia type 56 or SPG56. The disease is caused by mutations in the CYP2U1 gene, which plays a role in fatty acid metabolism in the brain and nervous system. People with SPG56 typically develop symptoms in early childhood, though the age of onset can vary. The hallmark feature is spasticity — an abnormal tightness or stiffness in the leg muscles — which leads to difficulty walking and problems with balance. Over time, the stiffness may worsen, and some individuals may also develop intellectual disability, speech difficulties, seizures, and thinning of the corpus callosum (the structure connecting the two halves of the brain). Some patients also experience dystonia, which involves involuntary muscle contractions causing abnormal postures. There is currently no cure for SPG56. Treatment focuses on managing symptoms and improving quality of life. Physical therapy, medications to reduce spasticity (such as baclofen or tizanidine), and assistive devices like braces or wheelchairs are commonly used. Occupational therapy and speech therapy may also be helpful depending on the individual's needs. Research is ongoing to better understand the disease and develop new therapies.

Also known as:

Key symptoms:

Progressive leg stiffness (spasticity)Difficulty walkingBalance problemsIntellectual disabilitySpeech difficultiesSeizuresInvoluntary muscle contractions (dystonia)Thinning of the brain's connecting structure (thin corpus callosum)Abnormal brain white matter changesExaggerated reflexesToe walkingMuscle weakness in the legsDelayed motor milestonesLearning difficulties

Clinical phenotype terms (14)— hover any for plain English
Abnormal globus pallidus morphologyHP:0002453
Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Childhood

Begins in childhood, roughly ages 1 to 12

Orphanet ↗OMIM ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for Autosomal recessive spastic paraplegia type 56.

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No specialists are currently listed for Autosomal recessive spastic paraplegia type 56.

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Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to Autosomal recessive spastic paraplegia type 56.

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Community

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Questions for your doctor

Bring these to your next appointment

  • Q1.What is the expected progression of symptoms in my child's specific case?,What therapies (physical, occupational, speech) should we start right away?,Are there any medications that can help with the leg stiffness or seizures?,Should other family members be tested for the CYP2U1 gene mutation?,Are there any clinical trials or research studies we could participate in?,What educational supports or accommodations should we request at school?,How often should we schedule follow-up appointments and brain imaging?

Common questions about Autosomal recessive spastic paraplegia type 56

What is Autosomal recessive spastic paraplegia type 56?

Autosomal recessive spastic paraplegia type 56 (SPG56) is a rare inherited neurological condition that primarily affects the nervous system, causing progressive stiffness and weakness in the legs. It is also known as hereditary spastic paraplegia type 56 or SPG56. The disease is caused by mutations in the CYP2U1 gene, which plays a role in fatty acid metabolism in the brain and nervous system. People with SPG56 typically develop symptoms in early childhood, though the age of onset can vary. The hallmark feature is spasticity — an abnormal tightness or stiffness in the leg muscles — which lead

How is Autosomal recessive spastic paraplegia type 56 inherited?

Autosomal recessive spastic paraplegia type 56 follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Autosomal recessive spastic paraplegia type 56 typically begin?

Typical onset of Autosomal recessive spastic paraplegia type 56 is childhood. Age of onset can vary across affected individuals.