Adult familial nephronophthisis-spastic quadriparesia syndrome

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Overview

Adult familial nephronophthisis-spastic quadriparesia syndrome (also known as adult nephronophthisis with spastic quadriplegia, or Mainzer-Saldino-like syndrome variant, Orphanet code 2666) is an extremely rare inherited condition that affects both the kidneys and the nervous system. In this syndrome, the kidneys gradually lose their ability to filter waste from the blood due to a condition called nephronophthisis, which causes scarring and cyst formation in the kidneys. At the same time, affected individuals develop spastic quadriparesis, which means increasing stiffness and weakness in all four limbs due to damage in the parts of the brain or spinal cord that control movement. Symptoms typically appear in adulthood, which is unusual because most forms of nephronophthisis begin in childhood. Patients may first notice increased thirst, frequent urination, and fatigue as their kidneys begin to fail. Over time, progressive stiffness and difficulty moving the arms and legs develop. Kidney function can decline to the point where dialysis or a kidney transplant is needed. There is currently no cure for this syndrome. Treatment focuses on managing kidney disease, including blood pressure control, dietary adjustments, and eventually renal replacement therapy such as dialysis or transplantation. The neurological symptoms are managed with physical therapy, medications to reduce muscle stiffness (spasticity), and supportive care. Because this condition is so rare, much of the management is guided by expert opinion and experience with related disorders rather than large clinical trials.

Key symptoms:

Progressive kidney failureIncreased thirst and frequent urinationStiffness in all four limbs (spastic quadriparesis)Difficulty walkingMuscle weakness in arms and legsFatigue and low energyHigh blood pressureAnemia related to kidney diseaseDifficulty with fine motor tasks like writing or buttoning clothesMuscle spasms or crampsSwelling in the legs or anklesPoor balance and coordination

Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Adult

Begins in adulthood (age 18 or older)

Orphanet ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for Adult familial nephronophthisis-spastic quadriparesia syndrome.

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No actively recruiting trials found for Adult familial nephronophthisis-spastic quadriparesia syndrome at this time.

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No specialists are currently listed for Adult familial nephronophthisis-spastic quadriparesia syndrome.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to Adult familial nephronophthisis-spastic quadriparesia syndrome.

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Community

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Caregiver Resources

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Questions for your doctor

Bring these to your next appointment

  • Q1.What stage is my kidney disease, and how quickly is it expected to progress?,Should I be evaluated for a kidney transplant, and when is the right time to start that process?,What medications can help with my muscle stiffness, and what are the side effects?,Are there genetic tests that could help identify the exact cause and help my family members understand their risk?,What dietary changes should I make to protect my kidneys?,How often should I have follow-up appointments and lab tests?,Are there any clinical trials or research studies I might be eligible for?

Common questions about Adult familial nephronophthisis-spastic quadriparesia syndrome

What is Adult familial nephronophthisis-spastic quadriparesia syndrome?

Adult familial nephronophthisis-spastic quadriparesia syndrome (also known as adult nephronophthisis with spastic quadriplegia, or Mainzer-Saldino-like syndrome variant, Orphanet code 2666) is an extremely rare inherited condition that affects both the kidneys and the nervous system. In this syndrome, the kidneys gradually lose their ability to filter waste from the blood due to a condition called nephronophthisis, which causes scarring and cyst formation in the kidneys. At the same time, affected individuals develop spastic quadriparesis, which means increasing stiffness and weakness in all f

How is Adult familial nephronophthisis-spastic quadriparesia syndrome inherited?

Adult familial nephronophthisis-spastic quadriparesia syndrome follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does Adult familial nephronophthisis-spastic quadriparesia syndrome typically begin?

Typical onset of Adult familial nephronophthisis-spastic quadriparesia syndrome is adult. Age of onset can vary across affected individuals.