46,XX difference of sex development-skeletal anomalies syndrome

Last reviewed

🖨 Print for my doctorAdvocacy Hub →
ORPHA:2975OMIM:264270Q56.2
Who is this for?
Show terms as
8Treatment centers

Where are you in your journey?

UniteRare data is sourced from FDA.gov, ClinicalTrials.gov, Orphanet, OMIM, and NORD.
Report missing data

Overview

46,XX difference of sex development-skeletal anomalies syndrome (also known as Nivelon-Nivelon-Mabille syndrome) is an extremely rare genetic condition that affects both sexual development and bone formation. In this syndrome, a person has female chromosomes (46,XX) but their body develops with ambiguous or atypical genitalia, meaning the external sex organs may not clearly appear male or female. This is combined with significant skeletal abnormalities, which can include problems with bone growth, abnormal shape of the spine or limbs, and other structural differences in the skeleton. Key features of this condition include ambiguous genitalia at birth, short stature, skeletal malformations (such as abnormalities of the vertebrae, limbs, or ribs), and sometimes intellectual disability or developmental delays. Some affected individuals may also have facial differences or other organ involvement. Because this syndrome is so rare, there is no specific cure. Treatment focuses on managing individual symptoms. This may include hormone therapy to support appropriate sexual development, orthopedic care for bone problems, surgical correction of genital or skeletal abnormalities when needed, and developmental support services. A team of specialists working together is essential for the best possible care. Early diagnosis and intervention can help improve quality of life.

Also known as:

Key symptoms:

Ambiguous genitalia at birthShort statureAbnormal bone developmentSpine abnormalitiesLimb malformationsIntellectual disabilityDevelopmental delaysUnusual facial featuresGrowth restriction before birthAbnormal rib formation

Clinical phenotype terms (12)— hover any for plain English
Ambiguous genitalia, femaleHP:0000061Fused labia minoraHP:0000063Dislocated radial headHP:0003083Deformed humerusHP:0003871Mandibular condyle hypoplasiaHP:0007628Hypoplasia of the premaxillaHP:0010650Increased size of the clitorisHP:0040253Abnormality of the ovaryHP:0000137Abnormal vagina morphologyHP:0000142
Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Neonatal

Begins at or shortly after birth (first 4 weeks)

Orphanet ↗OMIM ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for 46,XX difference of sex development-skeletal anomalies syndrome.

View clinical trials →

No actively recruiting trials found for 46,XX difference of sex development-skeletal anomalies syndrome at this time.

New trials open frequently. Follow this disease to get notified.

Search ClinicalTrials.gov ↗Join the 46,XX difference of sex development-skeletal anomalies syndrome community →

No specialists are currently listed for 46,XX difference of sex development-skeletal anomalies syndrome.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to 46,XX difference of sex development-skeletal anomalies syndrome.

Search all travel grants →NORD Financial Assistance ↗

Community

Open 46,XX difference of sex development-skeletal anomalies syndromeForum →

No community posts yet. Be the first to share your experience with 46,XX difference of sex development-skeletal anomalies syndrome.

Start the conversation →

Latest news about 46,XX difference of sex development-skeletal anomalies syndrome

No recent news articles for 46,XX difference of sex development-skeletal anomalies syndrome.

Follow this condition to be notified when news becomes available.

Caregiver Resources

NORD Caregiver Resources

Support, advocacy, and financial assistance for caregivers of rare disease patients.

Mental Health Support

Rare disease caregiving can be isolating. Connect with counseling and peer support.

Family & Caregiver Grants

Financial assistance programs specifically for caregivers of rare disease patients.

Social Security Disability

Learn how rare disease patients may qualify for SSDI/SSI benefits.

Questions for your doctor

Bring these to your next appointment

  • Q1.What specific skeletal and genital findings does my child have, and how severe are they?,Will my child need hormone therapy, and if so, when should it start?,What surgical options are available, and what are the risks and benefits of each?,Should we pursue genetic testing such as whole exome sequencing to look for a cause?,What developmental support services should we set up for my child?,How will this condition affect my child's growth, puberty, and fertility?,Are there other families or support groups we can connect with?

Common questions about 46,XX difference of sex development-skeletal anomalies syndrome

What is 46,XX difference of sex development-skeletal anomalies syndrome?

46,XX difference of sex development-skeletal anomalies syndrome (also known as Nivelon-Nivelon-Mabille syndrome) is an extremely rare genetic condition that affects both sexual development and bone formation. In this syndrome, a person has female chromosomes (46,XX) but their body develops with ambiguous or atypical genitalia, meaning the external sex organs may not clearly appear male or female. This is combined with significant skeletal abnormalities, which can include problems with bone growth, abnormal shape of the spine or limbs, and other structural differences in the skeleton. Key feat

How is 46,XX difference of sex development-skeletal anomalies syndrome inherited?

46,XX difference of sex development-skeletal anomalies syndrome follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.

At what age does 46,XX difference of sex development-skeletal anomalies syndrome typically begin?

Typical onset of 46,XX difference of sex development-skeletal anomalies syndrome is neonatal. Age of onset can vary across affected individuals.