46,XX difference of sex development-anorectal anomalies syndrome

Last reviewed

🖨 Print for my doctorAdvocacy Hub →
ORPHA:2973Q56.2
Who is this for?
Show terms as
8Treatment centers

Where are you in your journey?

UniteRare data is sourced from FDA.gov, ClinicalTrials.gov, Orphanet, OMIM, and NORD.
Report missing data

Overview

46,XX difference of sex development-anorectal anomalies syndrome (also known as Perineal scrotal hypospadias-anorectal anomalies syndrome, or sometimes referred to as 46,XX DSD with anorectal malformations) is an extremely rare condition that affects how the body develops before birth. In this syndrome, a person has female chromosomes (46,XX) but is born with differences in the development of their genitalia, meaning the external sex organs may not look typically male or female. This is called a difference of sex development (DSD). In addition, these individuals have problems with the formation of the anus and rectum (anorectal anomalies), which can range from a narrowed anal opening to a completely absent or misplaced anus. Some affected individuals may also have other birth differences involving the urinary tract or kidneys. Because this condition is present at birth, it is usually noticed right away by doctors during the newborn examination. The combination of ambiguous genitalia and anorectal malformations requires a team of specialists to evaluate and manage. Treatment typically involves surgical correction of the anorectal anomalies to allow normal bowel function, as well as careful evaluation and sometimes surgical management of the genital differences. Hormone therapy and psychological support may also be part of long-term care. The exact genetic cause of this syndrome is not fully understood, and research is ongoing to better define the underlying mechanisms.

Also known as:

Key symptoms:

Ambiguous genitalia (sex organs that do not look clearly male or female)Absent or misplaced anal openingNarrowed anal passageAbnormal connection between the rectum and urinary tract or genitals (fistula)Underdeveloped or absent uterusAbnormal development of the scrotum or labiaHypospadias (urinary opening in an unusual position)Kidney or urinary tract abnormalitiesDifficulty passing stoolConstipationPossible genital skin differences

Clinical phenotype terms (15)— hover any for plain English
HydroureterHP:0000072Abnormality of the urethraHP:0000795Abnormal internal genitaliaHP:0000812Female pseudohermaphroditismHP:0010458Displacement of the urethral meatusHP:0100627Urogenital sinus anomalyHP:0100779
Inheritance

Variable

Can be inherited in different ways depending on the underlying gene

Age of Onset

Neonatal

Begins at or shortly after birth (first 4 weeks)

Orphanet ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for 46,XX difference of sex development-anorectal anomalies syndrome.

View clinical trials →

No actively recruiting trials found for 46,XX difference of sex development-anorectal anomalies syndrome at this time.

New trials open frequently. Follow this disease to get notified.

Search ClinicalTrials.gov ↗Join the 46,XX difference of sex development-anorectal anomalies syndrome community →

No specialists are currently listed for 46,XX difference of sex development-anorectal anomalies syndrome.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to 46,XX difference of sex development-anorectal anomalies syndrome.

Search all travel grants →NORD Financial Assistance ↗

Community

Open 46,XX difference of sex development-anorectal anomalies syndromeForum →

No community posts yet. Be the first to share your experience with 46,XX difference of sex development-anorectal anomalies syndrome.

Start the conversation →

Latest news about 46,XX difference of sex development-anorectal anomalies syndrome

No recent news articles for 46,XX difference of sex development-anorectal anomalies syndrome.

Follow this condition to be notified when news becomes available.

Caregiver Resources

NORD Caregiver Resources

Support, advocacy, and financial assistance for caregivers of rare disease patients.

Mental Health Support

Rare disease caregiving can be isolating. Connect with counseling and peer support.

Family & Caregiver Grants

Financial assistance programs specifically for caregivers of rare disease patients.

Social Security Disability

Learn how rare disease patients may qualify for SSDI/SSI benefits.

Questions for your doctor

Bring these to your next appointment

  • Q1.What specific type of anorectal anomaly does my child have, and what surgery is recommended?,How will the differences in sex development be evaluated and managed over time?,Will my child need hormone therapy, and if so, when would it start?,What kind of bowel management program will my child need after surgery?,Are there genetic tests that could help us understand the cause of this condition?,What psychological support services are available for our family?,What is the long-term outlook for bowel control and quality of life?

Common questions about 46,XX difference of sex development-anorectal anomalies syndrome

What is 46,XX difference of sex development-anorectal anomalies syndrome?

46,XX difference of sex development-anorectal anomalies syndrome (also known as Perineal scrotal hypospadias-anorectal anomalies syndrome, or sometimes referred to as 46,XX DSD with anorectal malformations) is an extremely rare condition that affects how the body develops before birth. In this syndrome, a person has female chromosomes (46,XX) but is born with differences in the development of their genitalia, meaning the external sex organs may not look typically male or female. This is called a difference of sex development (DSD). In addition, these individuals have problems with the formatio

At what age does 46,XX difference of sex development-anorectal anomalies syndrome typically begin?

Typical onset of 46,XX difference of sex development-anorectal anomalies syndrome is neonatal. Age of onset can vary across affected individuals.