2-methylbutyryl-CoA dehydrogenase deficiency

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ORPHA:79157OMIM:610006E71.1
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Overview

2-methylbutyryl-CoA dehydrogenase deficiency (also called 2-methylbutyrylglycinuria or short/branched-chain acyl-CoA dehydrogenase deficiency, sometimes abbreviated as 2-MBD or SBCAD deficiency) is a rare inherited metabolic disorder. It affects the way the body breaks down a building block of protein called isoleucine. Normally, a specific enzyme called 2-methylbutyryl-CoA dehydrogenase helps process isoleucine in the body's cells. When this enzyme does not work properly, a substance called 2-methylbutyrylglycine builds up and is released in the urine. Many people with this condition have no symptoms at all and live healthy lives. However, some individuals — especially children — may experience low muscle tone (floppiness), feeding difficulties, low blood sugar, seizures, or developmental delays. Symptoms can sometimes be triggered by illness, fasting, or times of physical stress. The condition is often picked up through newborn screening programs before any symptoms appear. Treatment mainly focuses on managing diet and avoiding long periods without eating. A metabolic specialist can guide a low-isoleucine diet and recommend supplements if needed. With careful management, most people with this condition do well, though ongoing monitoring is important.

Also known as:

Key symptoms:

Low muscle tone (floppy muscles, especially in infants)Feeding difficulties in newborns or infantsLow blood sugar (hypoglycemia)Seizures or convulsionsDevelopmental delays (slower to reach milestones like sitting or walking)Intellectual disability (in some cases)Fatigue or low energyVomiting, especially during illnessUnusual smell in urinePoor weight gain or failure to thrive in infancy

Clinical phenotype terms (9)— hover any for plain English
Elevated circulating C5 acylcarnitine concentrationHP:00350192-ethylhydracylic aciduriaHP:0033220
Inheritance

Autosomal recessive

Passed on when both parents carry the same gene change; often skips generations

Age of Onset

Variable

Can begin at different ages, from infancy through adulthood

Orphanet ↗OMIM ↗NORD ↗

Treatments

No FDA-approved treatments are currently listed for 2-methylbutyryl-CoA dehydrogenase deficiency.

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No actively recruiting trials found for 2-methylbutyryl-CoA dehydrogenase deficiency at this time.

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No specialists are currently listed for 2-methylbutyryl-CoA dehydrogenase deficiency.

View NORD Rare Disease Centers ↗Undiagnosed Disease Network ↗

Treatment Centers

8 centers
🏥 NORD

Baylor College of Medicine Rare Disease Center

Baylor College of Medicine

📍 Houston, TX

🏥 NORD

Stanford Medicine Rare Disease Center

Stanford Medicine

📍 Stanford, CA

🔬 UDN

NIH Clinical Center Undiagnosed Diseases Program

National Institutes of Health

📍 Bethesda, MD

🔬 UDN

UCLA UDN Clinical Site

UCLA Health

📍 Los Angeles, CA

🔬 UDN

Baylor College of Medicine UDN Clinical Site

Baylor College of Medicine

📍 Houston, TX

🔬 UDN

Harvard/MGH UDN Clinical Site

Massachusetts General Hospital

📍 Boston, MA

🏥 NORD

Mayo Clinic Center for Individualized Medicine

Mayo Clinic

📍 Rochester, MN

👤 Mayo Clinic Center for Individualized Medicine

🏥 NORD

UCLA Rare Disease Day Program

UCLA Health

📍 Los Angeles, CA

Travel Grants

No travel grants are currently matched to 2-methylbutyryl-CoA dehydrogenase deficiency.

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Community

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Caregiver Resources

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Questions for your doctor

Bring these to your next appointment

  • Q1.Does my child need to follow a special diet, and how strict does it need to be?,What should I do if my child gets sick and cannot eat — do you have a written sick day plan for us?,How often should we have follow-up appointments and what tests will be done?,Are there any signs of a metabolic crisis I should watch for, and when should I go to the emergency room?,Should other family members be tested for this condition?,Will this condition affect my child's development or learning, and what support is available?,Are there any clinical trials or new treatments we should know about?

Common questions about 2-methylbutyryl-CoA dehydrogenase deficiency

What is 2-methylbutyryl-CoA dehydrogenase deficiency?

2-methylbutyryl-CoA dehydrogenase deficiency (also called 2-methylbutyrylglycinuria or short/branched-chain acyl-CoA dehydrogenase deficiency, sometimes abbreviated as 2-MBD or SBCAD deficiency) is a rare inherited metabolic disorder. It affects the way the body breaks down a building block of protein called isoleucine. Normally, a specific enzyme called 2-methylbutyryl-CoA dehydrogenase helps process isoleucine in the body's cells. When this enzyme does not work properly, a substance called 2-methylbutyrylglycine builds up and is released in the urine. Many people with this condition have no

How is 2-methylbutyryl-CoA dehydrogenase deficiency inherited?

2-methylbutyryl-CoA dehydrogenase deficiency follows a autosomal recessive inheritance pattern. Genetic counseling can help families understand recurrence risk and testing options.